Givinostat Evidence: Trial Results and Peer-Reviewed Publications

Hipa.ai Research · Source: PubMed & ClinicalTrials.gov / AACT · Last updated:

The clinical evidence base for Givinostat comprises 4 peer-reviewed publications across 4 journals, 1 pivotal-trial primary-outcome rows reported to ClinicalTrials.gov, spanning indications including Muscular Dystrophy, Duchenne. Most recent publication: Long-Term Evaluation of Givinostat in Duchenne Muscular Dystrophy, and Natural History Comparisons., Ann Clin Transl Neurol, 2025.

Top peer-reviewed publications

Curated set of pivotal-trial result papers and recent publications in high-tier journals.

  1. Histological effects of givinostat in boys with Duchenne muscular dystrophy.
    Bettica P, Petrini S, D'Oria V, et al. · Neuromuscul Disord · 2018
    PubMed: PMID 27566866 · NCT01761292 · Muscular Dystrophy, Duchenne
  2. Safety and efficacy of givinostat in boys with Duchenne muscular dystrophy (EPIDYS): a multicentre, randomised, double-blind, placebo-controlled, phase 3 trial.
    Mercuri E, Vilchez JJ, Boespflug-Tanguy O, et al. · Lancet Neurol · 2024
    PubMed: PMID 38508835 · NCT02851797 · Muscular Dystrophy, Duchenne
  3. Long-Term Evaluation of Givinostat in Duchenne Muscular Dystrophy, and Natural History Comparisons.
    McDonald CM, Guglieri M, Vučinić D, et al. · Ann Clin Transl Neurol · 2025
    PubMed: PMID 40830818 · NCT03373968 · Muscular Dystrophy, Duchenne
  4. Preclinical studies in the mdx mouse model of duchenne muscular dystrophy with the histone deacetylase inhibitor givinostat.
    Consalvi S, Mozzetta C, Bettica P, et al. · Mol Med · 2013
    PubMed: PMID 23552722 · NCT05933057 (ULYSSES) · Muscular Dystrophy, Duchenne

Primary-outcome results across pivotal trials

Per-arm reported values from Phase 2/3 and Phase 3 trials with results posted to ClinicalTrials.gov.

TrialIndicationPrimary endpointArmValue
NCT02851797Muscular Dystrophy, DuchenneMean Change From Baseline in 4 Standard Stairs (4SC) Climb After 18 Months of Treatment
Baseline and 18 months
Givinostat1.27 seconds (±0.040 Standard Error)
Placebo1.48 seconds (±0.058 Standard Error)

Publications by year

20132025: 4 publications.

2013
1
2018
1
2024
1
2025
1

Publications by indication

Muscular Dystrophy, Duchenne (4)

  • Long-Term Evaluation of Givinostat in Duchenne Muscular Dystrophy, and Natural History Comparisons.
    Ann Clin Transl Neurol · 2025 · PMID 40830818 · NCT03373968
  • Safety and efficacy of givinostat in boys with Duchenne muscular dystrophy (EPIDYS): a multicentre, randomised, double-blind, placebo-controlled, phase 3 trial.
    Lancet Neurol · 2024 · PMID 38508835 · NCT02851797
  • Histological effects of givinostat in boys with Duchenne muscular dystrophy.
    Neuromuscul Disord · 2018 · PMID 27566866 · NCT01761292
  • Preclinical studies in the mdx mouse model of duchenne muscular dystrophy with the histone deacetylase inhibitor givinostat.
    Mol Med · 2013 · PMID 23552722 · NCT05933057

Publications by journal

Trial-results highlights

For individuals with Duchenne Muscular Dystrophy, the clinical evidence for Givinostat includes results from a pivotal trial. In NCT02851797, a study investigating Duchenne Muscular Dystrophy, the primary outcome measured was the mean change from baseline in the 4 Standard Stairs Climb (4SC) after 18 months of treatment. In the Givinostat arm of NCT02851797, the mean change from baseline in 4SC climb was 1.27 seconds (least squares mean) after 18 months of treatment. In the placebo arm of NCT02851797, the mean change from baseline in 4SC climb was 1.48 seconds (least squares mean) after 18 months of treatment.

All values are sourced from primary registry reporting; individual papers should be consulted for clinical decisions.

All Givinostat publications (4)

2025 (1 paper)

  1. Long-Term Evaluation of Givinostat in Duchenne Muscular Dystrophy, and Natural History Comparisons.
    McDonald CM, Guglieri M, Vučinić D, et al. · Ann Clin Transl Neurol · 2025 · Derived
    PubMed: PMID 40830818 · NCT03373968 · Muscular Dystrophy, Duchenne

2024 (1 paper)

  1. Safety and efficacy of givinostat in boys with Duchenne muscular dystrophy (EPIDYS): a multicentre, randomised, double-blind, placebo-controlled, phase 3 trial.
    Mercuri E, Vilchez JJ, Boespflug-Tanguy O, et al. · Lancet Neurol · 2024 · Derived
    PubMed: PMID 38508835 · NCT02851797 · Muscular Dystrophy, Duchenne

2018 (1 paper)

  1. Histological effects of givinostat in boys with Duchenne muscular dystrophy.
    Bettica P, Petrini S, D'Oria V, et al. · Neuromuscul Disord · 2018 · Trial result
    PubMed: PMID 27566866 · NCT01761292 · Muscular Dystrophy, Duchenne

2013 (1 paper)

  1. Preclinical studies in the mdx mouse model of duchenne muscular dystrophy with the histone deacetylase inhibitor givinostat.
    Consalvi S, Mozzetta C, Bettica P, et al. · Mol Med · 2013 · Background
    PubMed: PMID 23552722 · NCT05933057 (ULYSSES) · Muscular Dystrophy, Duchenne

Sources and methodology

This page summarizes published evidence for general reference and does not constitute medical advice. For clinical decisions, consult the linked primary publications and your healthcare provider. Data sourced from PubMed and the ClinicalTrials.gov / AACT database maintained by the Clinical Trials Transformation Initiative (CTTI).